Bozkurt, GulpembeJayan, GeorgeMahmutoglu, Abdullah Soydan2023-02-212023-02-212020-01-0110.14744/nci.2019.12844https://hdl.handle.net/11443/2068http://dx.doi.org/10.14744/nci.2019.12844Adenoid cystic carcinoma (ACC), regardless of the primary site, is typically characterized by a long clinical course associated with a high rate of distant metastases. Intracranial metastasis of ACC is a very rare entity with only few reported cases in the literature. In this study, we report an unusual case of extra-axial intracranial metastasis of ACC in the dura. The primary parotid gland tumour was resected 15 y back. No recurrence had been detected before the occurrence of extra-axial metastasis. After surgical decompression, palliative radiotherapy was administered. To our knowledge, this is the longest interval for the development of metastases following excision of a parotid adenoid cystic carcinoma. This case can raise awareness across specialties that patients with adenoid cystic carcinoma are still at risk of developing metastases even following specialist discharge.Adenoid cystic carcinomabrainstem compressiondistant metastasisextra-axial intracranial metastasisperineural invasionArticleWOS:000534635600016